A Rare Maxillary Case of Calcified Epithelial Odontogenic (Pindborg) Tumor in a Young Patient

Abstract

Aim The calcified epithelial odontogenic tumor (CEOT) is a rare, benign lesion, accounting for approximately 1% of odontogenic tumors. The primary treatment involves surgical excision, with a documented recurrence rate of 14%. This case report aims to contribute to the literature by presenting the radiological and histopathological findings, along with the surgical management, of a CEOT located in an unusual area in a female patient under 20 years old. Case Report An 18-year-old female patient was referred to our clinic due to an incidental lesion located between the left maxillary premolar teeth. A delayed positive response was noted in the cold vitality test performed on asymptomatic, caries-free premolars. Cone beam computed tomography (CBCT) revealed a radiolucent lesion between the premolars, displacing the root of tooth 24 buccally and expanding the palatal cortex, with central radiopacity. Under local anesthesia, a palatal mucoperiosteal flap was raised, and a window was created in the palatal cortex using a surgical bur. The lesion was then enucleated with a curette, and the flap was sutured. Histopathological analysis showed polyhedral tumor cells among large and small calcification islands, confirming a diagnosis of CEOT. Discussion Although treatment options may vary based on CEOT location and size, enucleation remains the most common approach. Conclusion Given the high recurrence rate, long-term follow-up is essential. The patient has been followed up every six months, with no recurrence observed over a two-year period.

Keywords

• Calcified epithelial odontogenic tumor
• Enucleation
• Liesegang rings
• Maxilla
• Pindborg tumor

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