MONOSTOTIC FIBROUS DYSPLASIA PRESENTING IN MAXILLA: A CASE REPORT

Abstract

Fibrous dysplasia (FD) is a bone disorder in which fibrous tissue replaces normal bone. FD can be monostotic (10%–25%) or polyostotic (50–90%) and is typically diagnosed accidentally on radiographs. Craniofacial lesions are typically unilateral and are diagnosed by clinical assessment and radiographic evaluation. This report describes the case of a 50-year old female patient who had presented with painless swelling of the right maxilla and was diagnosed with FD. Subsequent bone scintigraphy identified the lesion as monostotic. Based on the patient’s age and the radiographic data, contour correction was performed. However, 1 year after surgery, the lesion regrew and the treatment was repeated.

Keywords

• Fibrous displasia,monostotic; maxilla

References

1. Verma A, Jindal N, Singh V, Sethi P. Unusual presentation of monostatic fibrous dysplasia in zygoma. J Craniofac Surg 2013;24(6):e592-594.
2. Wu H, Yang L, Li S, Jin X, Xu J, Lu J, Zhang C, Teng L. Clinical characteristics of craniomaxillofacial fibrous dysplasia. J Craniomaxillofac Surg 2014;42(7):1450-1455.
3. Anitha N, Sankari SL, Malathi L, Karthick R. Fibrous dysplasia - Recent concepts. J Pharm Bioalliedn Sci 2015;7(Suppl 1):S171-172.
4. Li J, Li H, Liu X, Han Z. Surgical treatment of polyostotic craniomaxillofacial fibrous dysplasia in adults: a case report and review of the literature. Int J Clin Exp Med 2015;15;8(9):16756-16764.
5. Wei WB, Chen MJ, Yang C, Zhang W, Wang Y. Decompression of the inferior alveolar nerve to treat the pain of the mandible caused by fibrous dysplasia - Case report. Int J Clin Exp Med 2015;8(10):19535-19539.
6. Nityasri V, Haris PS, Bose T, Balan A. Fibrous dysplasia - A 13-year retrospective radiographic analysis in a south Indian population. Dentomaxillofac Radiol 2011;40(5):282-289.
7. Hakim DN, Pelly T, Kulendran M, Caris JA. Benign tumours of the bone: A review. J Bone Oncol 2015;2;4(2):37-41.
8. Lietman SA, Levine MA. Fibrous dysplasia. Pediatr Endocrinol Rev 2013;10 Suppl 2(389-396).

9. De Melo WM, Sonoda CK, Hochuli-Vieira E. Monostotic fibrous dysplasia of the mandible. J Craniofac Surg 2012;23(5):e452-454.
10. Neville BW DD, Allen CM, Bouquot JE. Oral and maxillofacial pathology. St. Louis, Missouri: Saunders Elsevier, 2009, p.635-640.
11. Tsakiropoulou E, Konstantinidis I, Chatziavramidis A, Constantinidis J. Olfactory dysfunction as the first presenting symptome of cranial fibrous dysplasia. BMJ Case Rep. 2013, 26;2013. pii: bcr2013200432. doi: 10.1136/bcr-2013-200432
12. Chandar VV, Priya, Amita. Bilateral fibrous dysplasia of the mandible in a 7-year-old male patient - A rare case. J Indian Soc Pedod Prev Dent 2010;28(2):126-129.
13. Nair PP, Bhargava D, Thomas S, Shreenivas K. Immature fibrous dysplasia: A mixed radio-opaque radiolucent lesion. BMJ Case Rep 2013;3:2013. doi: 10.1136/bcr-2012-007934.
14. Park HJ, Cho MS, Lee SS. Fibrous dysplasia of the inferior turbinate. Int J Clin Exp Pathol 2013;6(3):531-535.