Öz
Ligneous conjunctivitis is a disease usually
characterized by type 1 plasminogen deficiency. As
well as being inherited, it may also be associated
with infection or trauma. It is characterized by the
woody appearance of pseudo-membranes rich in
fibrin, especially seen in the tarsal conjunctiva. İn
its treatment heparin, alpha chymotrypsin, topical
hyaluronidase, corticosteroids, cyclosporine, and
surgical excision of membranes exist. In this study, we
aimed to demonstrate the association of hydrocephalus
and ligneous conjunctivitis in a 10-month-old male
patient who had a ventricular-peritoneal shunt for
hydrocephalus.
Anahtar Kelimeler
Kaynakça
- Aslan AT1 Ozcelik U, Dogru D, Olmez A, Turanli G, Yalcin E, Kiper N, Tefs K, Schuster V. Congenital hydrocephalus as a rare association with ligneous conjunctivitis and type I plasminogen deficiency. Neuropediatrics 2005 Apr;36(2):108-11
- Hidayat AA, Riddle PJ. Ligneous conjunctivitis. A clinicopathologic study of 17 cases. Ophthalmology 1987; 94:949-59.
- Raimann, Rolf; Moya, Rene; Anguita, Rodrigo; Kobus, Rudolf; Pérez, Marcela; Gonzalez, Patricio (2018). Clinical, histopathological, and genetic aspects in one case of ligneous conjunctivitis, Ophthalmic Genetics, Doi: 10.1080/13816810.2018.1502791
- De Cock R. Membranaous, pseudomembranous and ligneous conjunctivitis. Dev Ophthalmol 1997; 28:32-45.
- Ozçelik U, Akçören Z, Anadol D, Kiper N, Orhon M, Göçmen A, et al. Pulmonary involvement in a child with ligneous conjunctivitis and homozygous type I plasminogen deficiency. Pediatr Pulmonol. 2001; 32:179–83
- Scully C, Gokbuget AY, Allen C, Bagan JV, Efeoglu A, Erseven G, et al. Oral lesions indicative of plasminogen deficiency (hypoplasminogenemia) Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2001; 91:334–7
- Scurry J, Planner R, Fortune DW, Lee CS, Rode J. Ligneous (pseudomembranous) inflammation of the female genital tract. A report of two cases. J Reprod Med. 1993; 38:407–12
- Azad N, Zafar S, Khan A. Succesful treatment of ligneous conjunctivitis with topical cyclosporine and heparine. J AAPOS 2009; 13:519-20.
- Coşkun M, Ayıntap E, Keskin U ve ark. Lignöz konjonktivitte membran eksizyonu sonrası topikal siklosporin A kullanılan iki olgu. Turkiye Klinikleri J Ophthalmol 2011; 20:162-5.
- Wakeling EL, Jolly M, Fisk NM, et al. X-linked inheritance of Dandy-Walker variant. Clin Dysmorphol 2002; 11:15–18.
- Srirampur A, Ramappa M, Chaurasia S, Vemuganti G. Indian J Ophthalmol. 2019 Jan;67(1):143-145. doi: 10.4103/ijo.IJO_772_18.
Öz
Lignöz konjoktivit, genellikle tip 1 plazminojen eksikliği
ile karakterize bir hastalıktır. Genetik kalıtımlı
olduğu gibi enfeksiyon veya travma ile de ilişkili
olabilir. Özellikle tarsal konjonktivada görülen odunsu
görünümde fibrinden zengin psödomembranlarla
karakterizedir. Tedavisinde; heparin, alfa kimotripsin,
topikal hiyalüronidaz, kortikosteroidler, siklosporin ve
membranların cerrahi eksizyonu yer almaktadır. Bu
çalışmada, hidrosefali nedeniyle ventrikülo-peritoneal
şant uygulanmış 10 aylık erkek hastada Dandy-
Walker spektrumuna bağlı hidrosefali ve lignöz
konjonktivit birlikteliğini göstermek amaçlanmıştır.
Anahtar Kelimeler
Kaynakça
- Aslan AT1 Ozcelik U, Dogru D, Olmez A, Turanli G, Yalcin E, Kiper N, Tefs K, Schuster V. Congenital hydrocephalus as a rare association with ligneous conjunctivitis and type I plasminogen deficiency. Neuropediatrics 2005 Apr;36(2):108-11
- Hidayat AA, Riddle PJ. Ligneous conjunctivitis. A clinicopathologic study of 17 cases. Ophthalmology 1987; 94:949-59.
- Raimann, Rolf; Moya, Rene; Anguita, Rodrigo; Kobus, Rudolf; Pérez, Marcela; Gonzalez, Patricio (2018). Clinical, histopathological, and genetic aspects in one case of ligneous conjunctivitis, Ophthalmic Genetics, Doi: 10.1080/13816810.2018.1502791
- De Cock R. Membranaous, pseudomembranous and ligneous conjunctivitis. Dev Ophthalmol 1997; 28:32-45.
- Ozçelik U, Akçören Z, Anadol D, Kiper N, Orhon M, Göçmen A, et al. Pulmonary involvement in a child with ligneous conjunctivitis and homozygous type I plasminogen deficiency. Pediatr Pulmonol. 2001; 32:179–83
- Scully C, Gokbuget AY, Allen C, Bagan JV, Efeoglu A, Erseven G, et al. Oral lesions indicative of plasminogen deficiency (hypoplasminogenemia) Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2001; 91:334–7
- Scurry J, Planner R, Fortune DW, Lee CS, Rode J. Ligneous (pseudomembranous) inflammation of the female genital tract. A report of two cases. J Reprod Med. 1993; 38:407–12
- Azad N, Zafar S, Khan A. Succesful treatment of ligneous conjunctivitis with topical cyclosporine and heparine. J AAPOS 2009; 13:519-20.
- Coşkun M, Ayıntap E, Keskin U ve ark. Lignöz konjonktivitte membran eksizyonu sonrası topikal siklosporin A kullanılan iki olgu. Turkiye Klinikleri J Ophthalmol 2011; 20:162-5.
- Wakeling EL, Jolly M, Fisk NM, et al. X-linked inheritance of Dandy-Walker variant. Clin Dysmorphol 2002; 11:15–18.
- Srirampur A, Ramappa M, Chaurasia S, Vemuganti G. Indian J Ophthalmol. 2019 Jan;67(1):143-145. doi: 10.4103/ijo.IJO_772_18.
Ayrıntılar
| Birincil Dil | Türkçe |
|---|---|
| Konular | Cerrahi |
| Bölüm | Olgu Sunumları |
| Yazarlar | |
| Yayımlanma Tarihi | 13 Eylül 2021 |
| Gönderilme Tarihi | 16 Ekim 2020 |
| Kabul Tarihi | 15 Şubat 2021 |
| Yayımlandığı Sayı | Yıl 2021 Cilt: 28 Sayı: 3 |
Süleyman Demirel Üniversitesi Tıp Fakültesi Dergisi/Medical Journal of Süleyman Demirel University is licensed under Creative Commons Attribution-NonCommercial-NoDerivs 4.0 International.