Abstract
Behçet’ s disease is a systemic autoimmune vasculitis of unknown etiology. It causes serious disability by affecting both arteries and veins. Hoarseness due to compression of the left recurrent laringeus nerve resulting from pathologies of the heart and intrathoracic great vessels is defined as Ortner’s syndrome. The most common cause of Ortner’s syndrome is left atrial enlargement due to mitral stenosis. Various intrathoracic pathologies may also be the reason. Beside, Ortner’s syndrome due to primary pulmonary artery aneurysm as a feature of Behçet’s disease is relatively rare. Herein, we report a case of a 78 year old female patient presenting with hoarseness and diagnosed as Ortner’s syndrome resulting from a giant pulmonary artery aneurysm secondary to Behçet’ s disease. J Clin Exp Invest 2015; 6 (1): 69-71 Key words: Ortner’ s Syndrome, Pulmonary Artery Aneurysm, Behçet’s Disease
Keywords
References
- Türkcü FM, Yüksel H, Uçmak D, et al. Demographic characteristics
- and ocular involvement in Behçet patients in
- Southeast Anatolia. J Clin Exp Invest 2013;4:339-342.
- Küçük A, Albayrak İ, Bağçacı S, Küçükşen S, Tunç R.
- Upper extremity thrombosis in Behçet. Dicle Med J
- ;40:507-509.
- Tüzün H, Hamuryudan V, Yıldırım S, et al. Surgical therapy
- of pulmonary arterial aneurysms in Behçet’s syndrome.
- Ann Thorac Surg 1996;61:733-735.
- Day JR, Walesby RK. A spontaneous ductal aneurysm
- presenting with left recurrent laryngeal nevre palsy. Ann
- Thorac Surg 2001;72:608-609.
- Kokotsakis J, Misthos P, Athanassiou T, et al. Acute Ortner’s
- syndrome arising from ductus arteriosus aneurysm.
- Tex Heart Inst J 2008;35:216-217.
- Shih HH, Kang PL, Lin CY, et al. Main pulmonary artery
- aneurysm. J Chin Med Assoc 2007;70:453-455.
- Imazio M, Cecchi E, Giammaria M, et al. Main pulmonary
- artery aneurysm: a case report and review of the literature.
- Ital Heart J 2004;5:232-237.
- Subramaniam V, Herle A, Mohammed N, et al. Ortner’s
- syndrome: case series and literature review. Braz J Otorhinolaryngol
- ;77:559-562.
- Mulpuru SK, Vasavada BC, Punukollu GK, et al. Cardiovocal
- syndrome: a systematic review. Heart Lung Circ
- ;17:1-4.
- Sakuma M, Demachi J, Suzuki J, et al. Proximal pulmonary
- artery aneurysms in patients with pulmonary
- artery hypertension: Complicated cases. Intern Med
- ;46:1789-1793.
- Bartter T, Irwin R, Nash G. Aneurysms of the pulmonary
- arteries. Chest 1988;94:1065-1075.
- Smalcelj A, Brida V, Samarzija M, et al. Giant, dissecting,
- high-pressure pulmonary artery aneurysm:
- case report of a 1-year natural course. Tex Heart Inst J
- ;32:589-594.
- Graham JK, Shehata B. Sudden death due to dissecting
- pulmonary artery aneurysm: a case report and review of
- the literature. Am J Forensic Med Pathol 2007;28:342-
- -
Ortner sendromu’ nun nadir bir nedeni: Behçet hastalığına sekonder gelişen dev pulmoner arter anevrizması
Abstract
Behçet Hastalığı nedeni bilinmeyen sistemik bir otoimmün vaskülittir. Hem arterleri hem de venleri tutarak ciddi sorunlara neden olabilir. Kalp ve intratorasik büyük damarların patolojilerine bağlı olarak sol rekürren laringeal sinirin kompresyonu sonucu gelişen ses kısıklığı Ortner Sendromu olarak ifade edilir. Ortner Sendromu’ nun en sık nedeni mitral darlığa bağlı olarak sol atriyum genişlemesidir. Çeşitli intratorasik patolojiler bu tablonun nedeni olabilir. Bununla birlikte Behçet Hastalığı sonucu gelişen pulmoner arter anevrizmasına bağlı Ortner Sendromu nispeten nadirdir. Biz burada ses kısıklığı ile başvuran ve yapılan incelemeler sonucunda Behçet Hastalığı’ na bağlı dev pulmoner arter anevrizması sonucu gelişen Ortner Sendromu olarak tanı alan 78 yaşında bir bayan hastayı sunuyoruz
References
- Türkcü FM, Yüksel H, Uçmak D, et al. Demographic characteristics
- and ocular involvement in Behçet patients in
- Southeast Anatolia. J Clin Exp Invest 2013;4:339-342.
- Küçük A, Albayrak İ, Bağçacı S, Küçükşen S, Tunç R.
- Upper extremity thrombosis in Behçet. Dicle Med J
- ;40:507-509.
- Tüzün H, Hamuryudan V, Yıldırım S, et al. Surgical therapy
- of pulmonary arterial aneurysms in Behçet’s syndrome.
- Ann Thorac Surg 1996;61:733-735.
- Day JR, Walesby RK. A spontaneous ductal aneurysm
- presenting with left recurrent laryngeal nevre palsy. Ann
- Thorac Surg 2001;72:608-609.
- Kokotsakis J, Misthos P, Athanassiou T, et al. Acute Ortner’s
- syndrome arising from ductus arteriosus aneurysm.
- Tex Heart Inst J 2008;35:216-217.
- Shih HH, Kang PL, Lin CY, et al. Main pulmonary artery
- aneurysm. J Chin Med Assoc 2007;70:453-455.
- Imazio M, Cecchi E, Giammaria M, et al. Main pulmonary
- artery aneurysm: a case report and review of the literature.
- Ital Heart J 2004;5:232-237.
- Subramaniam V, Herle A, Mohammed N, et al. Ortner’s
- syndrome: case series and literature review. Braz J Otorhinolaryngol
- ;77:559-562.
- Mulpuru SK, Vasavada BC, Punukollu GK, et al. Cardiovocal
- syndrome: a systematic review. Heart Lung Circ
- ;17:1-4.
- Sakuma M, Demachi J, Suzuki J, et al. Proximal pulmonary
- artery aneurysms in patients with pulmonary
- artery hypertension: Complicated cases. Intern Med
- ;46:1789-1793.
- Bartter T, Irwin R, Nash G. Aneurysms of the pulmonary
- arteries. Chest 1988;94:1065-1075.
- Smalcelj A, Brida V, Samarzija M, et al. Giant, dissecting,
- high-pressure pulmonary artery aneurysm:
- case report of a 1-year natural course. Tex Heart Inst J
- ;32:589-594.
- Graham JK, Shehata B. Sudden death due to dissecting
- pulmonary artery aneurysm: a case report and review of
- the literature. Am J Forensic Med Pathol 2007;28:342-
- -
Details
| Primary Language | English |
|---|---|
| Journal Section | Case Report |
| Authors | |
| Publication Date | May 10, 2015 |
| Published in Issue | Year 2015 Volume: 6 Issue: 1 |