Idiopatic Infantile Arterial Calcification: Echocardiography Diagnosis and Successful Treatment

Yıl 2019, Cilt: 2 Sayı: 1, 27 - 28, 15.10.2019

Hasan Onal Neval Topal Melek Yıldız Banu Aydın Aygün Dindar

Öz

Idiopathic
infantile arterial calcification is
rare disease characterized by medial calcification and intimal proliferation of
large and medium size arteries (1).

Prenatal prezantation is usually with nonimmune
hidrops and polyhydamnios (2). Although the clinical characteristics in
neonatal period is variable, respiratory distress with cardiac failure is the
most common finding. Hypertension due to poor compliance caused by diffuse
arterial calcification of the vessels is present in most patients.

Clinical experience in treating this rare disorder is
limited. We present a neonatal case with Idiopathic infantile
arterial calcification
who was treated with etidronate disodium, successfully.

Anahtar Kelimeler

Arterial Calcification

Kaynakça

• 1. Juul S, Ledbetter, Wight TN, Woodrum D. New insight into idiopathic infantile arterial calcinosis. Am J Dis Child. 144(2):229-33.
• 2. Nagar AM, Hanchate V, Tandon A, Thakkar H, Chaubal NG. Antenatal detection of idiopathic arterial calcification with hidrops fetalis. J Ultrasound Med 2003; 22(6): 653-9.
• 3. Bryant JH, White WA. A case of calcification of the arteries and obliterative endarteritis associated with hydronephrosis in child aged 6 months. Guys Hosp Rep 1901; 55: 17-28.
• 4. Samon LM, Ash KM, Murdison KA. Aorto-pulmonary calcification: an unusual manifestation of idiopathic calcification of infancy evident antenatally. Obstet Gynecol 1995; 85: 863-5.
• 5. Vera J, Lucaya J, Garcia Conesa JA, Aso C, Balaguer A. Idiopathic infantile arterial calcification: unusual features. Pediatr Radiol 1990; 20(8): 585-7.
• 6. Ciana G, Colonna F, Forleo V, Brizzi F, Benettoni A, de Vonderweid U. Idiopathic arterial calcification of infancy: effectiveness of prostaglandin infusion for treatment of secondary hypertension refractory to conventional therapy: case report. Pediatr Cardiol 1997; 18(1): 67-71.
• 7. Sholler GF, Yu JS, Bale PM, Hawker RE, Celermajer JM, Kozlowski K.. Generalized arterial calcification of infancy: three case reports, including spontaneous regression J Pediatr 1984; 105(2): 257-60.
• 8. von Bickel E, Janssen W. Arteriopathic calcifications infantum. Arch Kinderheilk. Unde 1963; 169: 274-85.
• 9. Meradji M, de Villenueve VH, Huber J, de Bruijn WC, Pearse RG. Idiopathic infantile arterial calcification in siblings: radiologic diagnosis and successful treatment. J Pedaitr 1978; 92: 401-5.
• 10. Stuart G, Wren C, Bain H. Idiopathic infantile arterial calcification in two siblings: failure of treatment with diphosphonate. Br Heart J 1990; 64(2): 156-9.