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Pseudohypoparathyroidism and Seizure: A Rare Case Report

Cilt: 3 Sayı: 2 17 Ağustos 2018
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Pseudohypoparathyroidism and Seizure: A Rare Case Report

Öz

Pseudohypoparathyroidism is characterized by hypocalcemia, hyperphosphatemia, increased serum parathyroid hormone values and insensitivity to the biological activity of parathyroid hormone. Pseudohypoparathyroidism is often associated with a characteristic phenotype known as Albright‘s hereditary osteodystrophy. Pseudohypoparathyroidism usually presents at an early age. We describe a 50-year-old man who presented with seizure due to hypocalcemia. He has typical features of Albright's hereditary osteodystrophy, which include a round face, short neck and stature.  Diffuse calsifications were seen on the bilateral cerebellum, putamen and dentate nucleus in computerized tomography. The patient is treated successfully by calcium carbonate and calcitriol supplementation This case was reported in order to remind pseudohypoparathyroidism in patients with hypocalcemic seizures.

Anahtar Kelimeler

Kaynakça

  1. Melmed S, Polonsky KS, Larsen PR, Kronenberg HM. Williams Textbook of Endocrinology. In: Bringhurst FR, Demay MB, Kronenberg HM. Hormones and disorders of mineral metabolism. Saunders, Philadelphia, 2011;1280-1283.
  2. Liu J, Erlichman B, Weinstein LS. The stimulatory G protein alpha-subunit Gs alpha is imprinted in human thyroid glands: implications for thyroid function in pseudohypoparathyroidism types 1A and 1B. J Clin Endocrinol Metab 2003;88:4336–4341
  3. Mantovani G. Pseudohypoparathyroidism: diagnosis and treatment. The Journal of Clinical Endocrinology & Metabolism 2011;96:3020-3030.
  4. Donghi V, Mora S, Zamproni I, Chiumello G, Weber G. Pseudohypoparathyroidism, an often delayed diagnosis: a case series. Cases J 2009;2:6734.
  5. Seki T, Yamamoto M, Kimura H, Tsuiki M, Ono M, Miki N, Takano K, Sato K: Vitamin D deficiency in two young adults with biochemical findings resembling pseudohypoparathyroidism type I and type II. Endocr J 2010; 57:735-744.
  6. Melmed S, Polonsky KS, Larsen PR, Kronenberg HM. Williams Textbook of Endocrinology. In: Bringhurst FR, Demay MB, Kronenberg HM. Hormones and disorders of mineral metabolism. Saunders, Philadelphia, 2011;1280-1283.
  7. Liu J, Erlichman B, Weinstein LS. The stimulatory G protein alpha-subunit Gs alpha is imprinted in human thyroid glands: implications for thyroid function in pseudohypoparathyroidism types 1A and 1B. J Clin Endocrinol Metab 2003;88:4336–4341
  8. Mantovani G. Pseudohypoparathyroidism: diagnosis and treatment. The Journal of Clinical Endocrinology & Metabolism 2011;96:3020-3030.

Ayrıntılar

Birincil Dil

İngilizce

Konular

-

Bölüm

Olgu Sunumu

Yazarlar

Ferhat Gökay
KAYSERİ EĞİTİM VE ARAŞTIRMA HASTANESİ
Türkiye

Yasin Şimşek Bu kişi benim
KAYSERİ EĞİTİM VE ARAŞTIRMA HASTANESİ
Türkiye

Oğuzhan Sitki Dizdar Bu kişi benim
KAYSERİ EĞİTİM VE ARAŞTIRMA HASTANESİ
Türkiye

Yayımlanma Tarihi

17 Ağustos 2018

Gönderilme Tarihi

10 Ocak 2017

Kabul Tarihi

17 Ağustos 2018

Yayımlandığı Sayı

Yıl 2018 Cilt: 3 Sayı: 2

Kaynak Göster

APA
Gökay, F., Şimşek, Y., & Dizdar, O. S. (2018). Pseudohypoparathyroidism and Seizure: A Rare Case Report. Journal of Anatolian Medical Research, 3(2), 52-58. https://izlik.org/JA35GB63KH
AMA
1.Gökay F, Şimşek Y, Dizdar OS. Pseudohypoparathyroidism and Seizure: A Rare Case Report. JAMER. 2018;3(2):52-58. https://izlik.org/JA35GB63KH
Chicago
Gökay, Ferhat, Yasin Şimşek, ve Oğuzhan Sitki Dizdar. 2018. “Pseudohypoparathyroidism and Seizure: A Rare Case Report”. Journal of Anatolian Medical Research 3 (2): 52-58. https://izlik.org/JA35GB63KH.
EndNote
Gökay F, Şimşek Y, Dizdar OS (01 Ağustos 2018) Pseudohypoparathyroidism and Seizure: A Rare Case Report. Journal of Anatolian Medical Research 3 2 52–58.
IEEE
[1]F. Gökay, Y. Şimşek, ve O. S. Dizdar, “Pseudohypoparathyroidism and Seizure: A Rare Case Report”, JAMER, c. 3, sy 2, ss. 52–58, Ağu. 2018, [çevrimiçi]. Erişim adresi: https://izlik.org/JA35GB63KH
ISNAD
Gökay, Ferhat - Şimşek, Yasin - Dizdar, Oğuzhan Sitki. “Pseudohypoparathyroidism and Seizure: A Rare Case Report”. Journal of Anatolian Medical Research 3/2 (01 Ağustos 2018): 52-58. https://izlik.org/JA35GB63KH.
JAMA
1.Gökay F, Şimşek Y, Dizdar OS. Pseudohypoparathyroidism and Seizure: A Rare Case Report. JAMER. 2018;3:52–58.
MLA
Gökay, Ferhat, vd. “Pseudohypoparathyroidism and Seizure: A Rare Case Report”. Journal of Anatolian Medical Research, c. 3, sy 2, Ağustos 2018, ss. 52-58, https://izlik.org/JA35GB63KH.
Vancouver
1.Ferhat Gökay, Yasin Şimşek, Oğuzhan Sitki Dizdar. Pseudohypoparathyroidism and Seizure: A Rare Case Report. JAMER [Internet]. 01 Ağustos 2018;3(2):52-8. Erişim adresi: https://izlik.org/JA35GB63KH