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Meme Malignite Şüpheli Olan Olguda: Nadir Bir Deri Eki Tümörü Spiradenom

Yıl 2026, Cilt: 48 Sayı: 1, 148 - 154, 15.12.2025
https://doi.org/10.20515/otd.1671917

Öz

Spiradenomlar, ter bezlerinden kaynaklanan nadir ve iyi huylu kutanöz tümörlerdir. Memedeki ekrin spiradenom vakaları ise oldukça nadirdir ve literatürde yalnızca birkaç vaka bildirilmiştir. Olgumuzda, annesi meme kanseri nedeniyle cerrahi müdahale geçiren 24 yaşında bir kadın hasta, sol memede ağrı ve şişlik şikayetleriyle başvurmuştur. Hastanın meme ultrasonografisi, meme manyetik rezonans görüntüleme ve tru-cut biyopsi sonuçlarında malignite açısından şüpheli bulgular saptanmıştır. Kesin tanı için cerrahi ekzisyon biyopsisi yapılmış ve patolojik incelemede deri eki tümörü olarak spiradenom ön planda raporlanmıştır. Literatürde, meme malignite şüphesi yüksek olan vakalarda spiradenom daha önce rapor edilmemiştir. Bu tür vakalarda, sınır negatifliği göz önünde bulundurularak yapılan cerrahi rezeksiyonun hastanın küratif tedavisini sağladığı vurgulanmaktadır.

Kaynakça

  • 1. Ribeiro-Silva A, Shaletich C, Careta RS, Kazava DK, Siqueira MC, Ponton F. Spiradenocarcinoma of the breast arising in a long-standing spiradenoma. Ann Diagn Pathol. 2004;8(3):162-6.
  • 2. Bosch MM, Boon ME. Fine-needle cytology of an eccrine spiradenoma of the breast: diagnosis made by a holistic approach. Diagn Cytopathol. 1992;8(4):366-8.
  • 3. Dick M, Sharma A, Sharma P. Spiradenoma arising in the breast of a high-risk breast cancer patient and review of cases over 76 years. J Am Acad Dermatol. 2020;83(6):AB30.
  • 4. Matsumoto H, Takamatsu R, Abe N, Unesoko M, Zaha H, Ishii A, et al. Spiradenoma of the breast: a rare diagnostic pitfall in the evaluation of solid-basaloid breast lesions with a dual cell population. Virchows Arch. 2021;479(2):401-5.
  • 5. Mambo NC. Eccrine spiradenoma: Clinical and pathologic study of 49 tumors. J Cutan Pathol. 1983;10:312-20.
  • 6. Nath AK, Kumari R, Thappa DM. Eccrine spiradenoma with chondroid syringoma in Blaschkoid distribution. Indian J Dermatol Venereol Leprol. 2009;75:600.
  • 7. Yoshida Y. Multiple vascular eccrine spiradenomas: A case report and published work review of multiple eccrine spiradenomas. J Dermatol. 2010.
  • 8. Shaikh-Naidu N, Breitbart A. Eccrine spiradenoma of the upper extremity: case report and an algorithm for management. Eur J Plast Surg. 2003;26(3):160-3.
  • 9. Fehr A, Kovács A, Löning T, Frierson H Jr, van den Oord J, Stenman G. The MYB–NFIB gene fusion—a novel genetic link between adenoid cystic carcinoma and dermal cylindroma. J Pathol. 2011;224(3):322-7.
  • 10. Malignant eccrine spiradenoma. Am J Dermatopathol. 2003;25(3):254-7.
  • 11. Senol M, Ozcan C, Sasmaz S. Giant vascular eccrine spiradenoma. Int J Dermatol. 1998;37:221-3. doi:10.1046/j.1365-4362.1998.00461.x.
  • 12. Calonje E, Marušić Z. Tumours of Skin Appendages. In: Rook’s Textbook of Dermatology. John Wiley & Sons, Ltd; 2024. p. 1-60.
  • 13. Metovic J, Gallino C, Zanon E, Bussone R, Russo R, Vissio E, Annaratone L, Conti L, Papotti M, Cassoni P, Castellano I. Eccrine spiradenoma of the nipple: Case report, differential diagnosis and literature review. Histol Histopathol. 2019 Aug;34(8):909-915.
  • 14. Lee HH, Park SH, Choi HY, Park HK. Eccrine spiradenoma arising in the breast misdiagnosed as an epidermal inclusion cyst. Korean J Radiol. 2011 Mar-Apr;12(2):256-60.
  • 15. Olayinka O, Cox SE, Nasrazadani A, Resetkova E, Ivan D, Middleton LP. Invasive carcinoma with skin adnexal trichilemmal hair follicular differentiation occurring in the breast: A case report with detailed immunohistochemical and molecular analysis. Int J Surg Pathol. 2024;32(4):796-802.
  • 16. Jin W, Kim GY, Lew BL, Yang DM, Kim HC, Ryu JK, et al. Sonographic findings of an eccrine spiradenoma. J Ultrasound Med. 2008;27(5):813-8.
  • 17. Funamizu N, Tabei I, Sekine C, Fuke A, Yabe M, Takeyama H, et al. Breast hemangioma with difficulty in preoperative diagnosis: a case report. World J Surg Oncol. 2014;12:313.
  • 18. Delfino S, Toto V, Brunetti B, Bianchi A, Baldi A, Persichetti P. Recurrent atypical eccrine spiradenoma of the forehead. In Vivo. 2008;22(6):821-3.
  • 19. De Andrés Gómez A, Navarro Moratalla C, Villalba Ferrer F, Sabater Marco V, García-Vilanova A, Fuster Diana C, Medrano González J, Palao Errando J. Malignant eccrine breast spiradenoma. A case report and literature review. Int J Surg Case Rep. 2015;15:81-4. doi: 10.1016/j.ijscr.2015.08.017. Epub 2015 Aug 18. PMID: 26318134; PMCID: PMC4601958.)
  • 20. Ter Poorten MC, Barrett K, Cook J. Familial eccrine spiradenoma: a case report and review of the literature. Dermatol Surg. 2003;29(4):411-4.
  • 21. Lee HH, Park SH, Choi HY, Park HK. Eccrine spiradenoma arising in the breast misdiagnosed as an epidermal inclusion cyst. Korean J Radiol. 2011;12(2):256-60.
  • 22. Płachta I, Kleibert M, Czarnecka AM, Spałek M, Szumera-Ciećkiewicz A, Rutkowski P. Current diagnosis and treatment options for cutaneous adnexal neoplasms with apocrine and eccrine differentiation. Int J Mol Sci. 2021;22(10):5077.
  • 23. Iida K, Iwai S, Hosaka H, Kitami Y, Akiyama M, Suzuki T, et al. Immunohistochemical characterization of non-epithelial cells in spiradenoma. J Dermatol. 2013;40(11):896-900.
  • 24. Alkan BI, Bozdogan O, Karadeniz M, Bozdoğan N. Two different cell populations is an important clue for diagnosis of primary cutaneous adenoid cystic carcinoma: immunohistochemical study. Case Rep Pathol. 2017;2017:7949361.
  • 25. Chang JY, Chen YC, Ding DC. Spiradenoma: a case report and review of the literature. Diagnostics. 2025;15(2):173.
  • 26. Metovic J, Gallino C, Zanon E, Bussone R, Russo R, Vissio E, et al. Eccrine spiradenoma of the nipple: case report, differential diagnosis and literature review. 2019.
  • 27. Maiorana A, Nigrisoli E, Papotti M. Immunohistochemical markers of sweat gland tumors. J Cutan Pathol. 1986;13(3):187-96.
  • 28. Ahmed MB, Elzawawi KE, AlHammadi A, Al-Malki A, Petkar M, Al Lahham S, et al. A malignant spiradenoma of the forehead: a case report and literature review. Oxford Med Case Rep. 2024;2024(3):omae016.

A Case With Suspected Breast Malignancy: A Rare Skin Appendage Tumor Spiradenoma

Yıl 2026, Cilt: 48 Sayı: 1, 148 - 154, 15.12.2025
https://doi.org/10.20515/otd.1671917

Öz

Spiradenomlar, ter bezlerinden kaynaklanan nadir ve iyi huylu kutanöz tümörlerdir. Memedeki ekrin spiradenom vakaları ise oldukça nadirdir ve literatürde yalnızca birkaç vaka bildirilmiştir. Olgumuzda, annesi meme kanseri nedeniyle cerrahi müdahale geçiren 24 yaşında bir kadın hasta, sol memede ağrı ve şişlik şikayetleriyle başvurmuştur. Hastanın meme ultrasonografisi, meme manyetik rezonans görüntüleme ve tru-cut biyopsi sonuçlarında malignite açısından şüpheli bulgular saptanmıştır. Kesin tanı için cerrahi ekzisyon biyopsisi yapılmış ve patolojik incelemede deri eki tümörü olarak spiradenom ön planda raporlanmıştır. Literatürde, meme malignite şüphesi yüksek olan vakalarda spiradenom daha önce rapor edilmemiştir. Bu tür vakalarda, sınır negatifliği göz önünde bulundurularak yapılan cerrahi rezeksiyonun hastanın küratif tedavisini sağladığı vurgulanmaktadır.

Kaynakça

  • 1. Ribeiro-Silva A, Shaletich C, Careta RS, Kazava DK, Siqueira MC, Ponton F. Spiradenocarcinoma of the breast arising in a long-standing spiradenoma. Ann Diagn Pathol. 2004;8(3):162-6.
  • 2. Bosch MM, Boon ME. Fine-needle cytology of an eccrine spiradenoma of the breast: diagnosis made by a holistic approach. Diagn Cytopathol. 1992;8(4):366-8.
  • 3. Dick M, Sharma A, Sharma P. Spiradenoma arising in the breast of a high-risk breast cancer patient and review of cases over 76 years. J Am Acad Dermatol. 2020;83(6):AB30.
  • 4. Matsumoto H, Takamatsu R, Abe N, Unesoko M, Zaha H, Ishii A, et al. Spiradenoma of the breast: a rare diagnostic pitfall in the evaluation of solid-basaloid breast lesions with a dual cell population. Virchows Arch. 2021;479(2):401-5.
  • 5. Mambo NC. Eccrine spiradenoma: Clinical and pathologic study of 49 tumors. J Cutan Pathol. 1983;10:312-20.
  • 6. Nath AK, Kumari R, Thappa DM. Eccrine spiradenoma with chondroid syringoma in Blaschkoid distribution. Indian J Dermatol Venereol Leprol. 2009;75:600.
  • 7. Yoshida Y. Multiple vascular eccrine spiradenomas: A case report and published work review of multiple eccrine spiradenomas. J Dermatol. 2010.
  • 8. Shaikh-Naidu N, Breitbart A. Eccrine spiradenoma of the upper extremity: case report and an algorithm for management. Eur J Plast Surg. 2003;26(3):160-3.
  • 9. Fehr A, Kovács A, Löning T, Frierson H Jr, van den Oord J, Stenman G. The MYB–NFIB gene fusion—a novel genetic link between adenoid cystic carcinoma and dermal cylindroma. J Pathol. 2011;224(3):322-7.
  • 10. Malignant eccrine spiradenoma. Am J Dermatopathol. 2003;25(3):254-7.
  • 11. Senol M, Ozcan C, Sasmaz S. Giant vascular eccrine spiradenoma. Int J Dermatol. 1998;37:221-3. doi:10.1046/j.1365-4362.1998.00461.x.
  • 12. Calonje E, Marušić Z. Tumours of Skin Appendages. In: Rook’s Textbook of Dermatology. John Wiley & Sons, Ltd; 2024. p. 1-60.
  • 13. Metovic J, Gallino C, Zanon E, Bussone R, Russo R, Vissio E, Annaratone L, Conti L, Papotti M, Cassoni P, Castellano I. Eccrine spiradenoma of the nipple: Case report, differential diagnosis and literature review. Histol Histopathol. 2019 Aug;34(8):909-915.
  • 14. Lee HH, Park SH, Choi HY, Park HK. Eccrine spiradenoma arising in the breast misdiagnosed as an epidermal inclusion cyst. Korean J Radiol. 2011 Mar-Apr;12(2):256-60.
  • 15. Olayinka O, Cox SE, Nasrazadani A, Resetkova E, Ivan D, Middleton LP. Invasive carcinoma with skin adnexal trichilemmal hair follicular differentiation occurring in the breast: A case report with detailed immunohistochemical and molecular analysis. Int J Surg Pathol. 2024;32(4):796-802.
  • 16. Jin W, Kim GY, Lew BL, Yang DM, Kim HC, Ryu JK, et al. Sonographic findings of an eccrine spiradenoma. J Ultrasound Med. 2008;27(5):813-8.
  • 17. Funamizu N, Tabei I, Sekine C, Fuke A, Yabe M, Takeyama H, et al. Breast hemangioma with difficulty in preoperative diagnosis: a case report. World J Surg Oncol. 2014;12:313.
  • 18. Delfino S, Toto V, Brunetti B, Bianchi A, Baldi A, Persichetti P. Recurrent atypical eccrine spiradenoma of the forehead. In Vivo. 2008;22(6):821-3.
  • 19. De Andrés Gómez A, Navarro Moratalla C, Villalba Ferrer F, Sabater Marco V, García-Vilanova A, Fuster Diana C, Medrano González J, Palao Errando J. Malignant eccrine breast spiradenoma. A case report and literature review. Int J Surg Case Rep. 2015;15:81-4. doi: 10.1016/j.ijscr.2015.08.017. Epub 2015 Aug 18. PMID: 26318134; PMCID: PMC4601958.)
  • 20. Ter Poorten MC, Barrett K, Cook J. Familial eccrine spiradenoma: a case report and review of the literature. Dermatol Surg. 2003;29(4):411-4.
  • 21. Lee HH, Park SH, Choi HY, Park HK. Eccrine spiradenoma arising in the breast misdiagnosed as an epidermal inclusion cyst. Korean J Radiol. 2011;12(2):256-60.
  • 22. Płachta I, Kleibert M, Czarnecka AM, Spałek M, Szumera-Ciećkiewicz A, Rutkowski P. Current diagnosis and treatment options for cutaneous adnexal neoplasms with apocrine and eccrine differentiation. Int J Mol Sci. 2021;22(10):5077.
  • 23. Iida K, Iwai S, Hosaka H, Kitami Y, Akiyama M, Suzuki T, et al. Immunohistochemical characterization of non-epithelial cells in spiradenoma. J Dermatol. 2013;40(11):896-900.
  • 24. Alkan BI, Bozdogan O, Karadeniz M, Bozdoğan N. Two different cell populations is an important clue for diagnosis of primary cutaneous adenoid cystic carcinoma: immunohistochemical study. Case Rep Pathol. 2017;2017:7949361.
  • 25. Chang JY, Chen YC, Ding DC. Spiradenoma: a case report and review of the literature. Diagnostics. 2025;15(2):173.
  • 26. Metovic J, Gallino C, Zanon E, Bussone R, Russo R, Vissio E, et al. Eccrine spiradenoma of the nipple: case report, differential diagnosis and literature review. 2019.
  • 27. Maiorana A, Nigrisoli E, Papotti M. Immunohistochemical markers of sweat gland tumors. J Cutan Pathol. 1986;13(3):187-96.
  • 28. Ahmed MB, Elzawawi KE, AlHammadi A, Al-Malki A, Petkar M, Al Lahham S, et al. A malignant spiradenoma of the forehead: a case report and literature review. Oxford Med Case Rep. 2024;2024(3):omae016.
Toplam 28 adet kaynakça vardır.

Ayrıntılar

Birincil Dil İngilizce
Konular Genel Cerrahi
Bölüm Olgu Sunumu
Yazarlar

Yasin Ekici 0000-0001-5758-8165

Bartu Badak 0000-0003-3465-8719

Nazlı Sena Seker 0000-0003-4588-7250

Gönderilme Tarihi 8 Nisan 2025
Kabul Tarihi 30 Temmuz 2025
Yayımlanma Tarihi 15 Aralık 2025
Yayımlandığı Sayı Yıl 2026 Cilt: 48 Sayı: 1

Kaynak Göster

Vancouver Ekici Y, Badak B, Seker NS. A Case With Suspected Breast Malignancy: A Rare Skin Appendage Tumor Spiradenoma. Osmangazi Tıp Dergisi. 2025;48(1):148-54.


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